Longitudinal Profiles of Expressive Vocabulary, Syntax and Pragmatic Language in Boys with Fragile X Syndrome or Down Syndrome

Autor/inn/en	Martin, Gary E.; Losh, Molly; Estigarribia, Bruno; Sideris, John; Roberts, Joanne
Titel	Longitudinal Profiles of Expressive Vocabulary, Syntax and Pragmatic Language in Boys with Fragile X Syndrome or Down Syndrome
Quelle	In: International Journal of Language & Communication Disorders, 48 (2013) 4, S.432-443 (12 Seiten) PDF als Volltext Verfügbarkeit
Sprache	englisch
Dokumenttyp	gedruckt; online; Zeitschriftenaufsatz
ISSN	1368-2822
DOI	10.1111/1460-6984.12019
Schlagwörter	Expressive Language; Vocabulary; Syntax; Pragmatics; Males; Down Syndrome; Genetic Disorders; Mental Age; Congenital Impairments; Autism; Pervasive Developmental Disorders; Language Impairments; Longitudinal Studies; Children; Comparative Analysis; Profiles; North Carolina; Leiter International Performance Scale; Autism Diagnostic Observation Schedule + Suchen Sie Ihr Suchwort? Wortschatz; Pragmalinguistik; Male; Männliches Geschlecht; 'Downs Syndrome; Down''s Syndrome'; Down-Syndrom; Geistige Beweglichkeit; Autismus; Speech disorder; Speech disorders; Speech disabilities; Speech disability; Speech handicap; Speech handicaps; Speech impairment; Speech impairments; Language handicaps; Sprachbehinderung; Longitudinal study; Longitudinal method; Longitudinal methods; Längsschnittuntersuchung; Child; Kind; Kinder; Charakterisierung; Profilanalyse
Abstract	Background: Fragile X syndrome (FXS) and Down syndrome (DS) are the two leading genetic causes of intellectual disability, and FXS is the most common known genetic condition associated with autism. Both FXS and DS are associated with significant language impairment, but little is known about expressive language across domains over time or the role of autism in language development in FXS. Aims: To compare three domains of language production (vocabulary, syntax, pragmatics) over time within and across groups of boys with FXS with and without autism spectrum disorder (FXS-ASD, FXS-O), boys with DS, and typically developing (TD) boys. Methods & Procedures: Twenty-nine boys with FXS-O, 40 boys with FXS-ASD, 34 boys with DS, and 48 younger TD boys of similar non-verbal mental age living in the United States participated in the study. The Antonyms, Syntax Construction and Pragmatic Judgment subtests of the Comprehensive Assessment of Spoken Language were administered annually over 3 years. Outcomes & Results: TD boys scored higher than all other groups on all three subtests; boys with FXS-O and FXS-ASD scored higher than boys with DS in Syntax Construction; and boys with FXS-O scored higher than boys with FXS-ASD in Pragmatic Judgment. Within-group patterns varied between groups. Overall, the TD group showed significantly more change over time than all other groups. Conclusions & Implications: Findings suggest that expressive language skills and growth across various domains are more impaired in boys with FXS and DS than would be expected based on non-verbal mental age, that for boys with DS syntax is more impaired than would be expected based on intellectual disability, and that autism status affects pragmatic language in boys with FXS. Findings suggest that language production across domains should be addressed during assessment and intervention for boys with FXS and boys with DS, with differing group profiles also suggesting potentially different areas of focus. (Contains 4 tables and 1 figure.) (As Provided).
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Erfasst von	ERIC (Education Resources Information Center), Washington, DC
Update	2017/4/10